CANDLE syndrome: a recently described autoinflammatory syndrome.
J Pediatr Hematol Oncol
; 37(4): 296-9, 2015 May.
Article
em En
| MEDLINE
| ID: mdl-25036278
CANDLE syndrome (chronic atypical neutrophilic dermatosis with lipodystrophy and elevated temperature) is a recently described autoinflammatory syndrome characterized by early onset, recurrent fever, skin lesions, and multisystemic inflammatory manifestations. Most of the patients have been shown to have mutation in PSMB8 gene. Herein, we report a 2-year-old patient with young onset recurrent fever, atypical facies, widespread skin lesions, generalized lymphadenopathy, hepatosplenomegaly, joint contractures, hypertrglyceridemia, lipodystrophy, and autoimmune hemolytic anemia. Clinical features together with the skin biopsy findings were consistent with the CANDLE syndrome. The pathogenesis and treatment of this syndrome have not been fully understood. Increased awareness of this recently described syndrome may lead to recognition of new cases and better understanding of its pathogenesis which in turn may help for development of an effective treatment.
Texto completo:
1
Base de dados:
MEDLINE
Assunto principal:
Dermatopatias
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Febre
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Inflamação
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Lipodistrofia
Tipo de estudo:
Etiology_studies
Limite:
Child, preschool
/
Humans
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Male
Idioma:
En
Revista:
J Pediatr Hematol Oncol
Assunto da revista:
HEMATOLOGIA
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NEOPLASIAS
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PEDIATRIA
Ano de publicação:
2015
Tipo de documento:
Article
País de afiliação:
Turquia