Late-onset transient adrenal insufficiency in preterm twins with twin-to-twin transfusion syndrome: A case report.
Medicine (Baltimore)
; 96(47): e8686, 2017 Nov.
Article
em En
| MEDLINE
| ID: mdl-29381949
ABSTRACT
RATIONALE Late-onset transient adrenal insufficiency with circulatory collapse is a rare condition that occurs in preterm infants. Although the incidence of late-onset transient adrenal insufficiency in preterm infants has been reported in Japan, reports from Western countries are lacking. In addition, no study has investigated the effect of twin-to-twin transfusion syndrome (TTTS) in monozygotic twins. PATIENT CONCERNS A pair of extremely low birth weight twins presented with TTTS. DIAGNOSES Both twins developed late-onset adrenal insufficiency with oliguria, hypotension, hyponatremia, and pulmonary edema at a postnatal age of 24 days and 51 days, respectively. INTERVENTION Temporary administration of intravenous hydrocortisone was initiated. OUTCOMES:
Their symptoms improved dramatically and they survived the event without any neurologic sequelae after 3 years of follow-up. LESSONS Late-onset circulatory collapse may occur, especially in extremely preterm infants, even at 2 months after birth. Hydrocortisone therapy is an effective treatment to rescue circulatory collapse caused by adrenal insufficiency in preterm infants and may not affect long-term neuromotor and cognitive outcomes.
Texto completo:
1
Base de dados:
MEDLINE
Assunto principal:
Choque
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Hidrocortisona
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Insuficiência Adrenal
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Lactente Extremamente Prematuro
Idioma:
En
Ano de publicação:
2017
Tipo de documento:
Article