Your browser doesn't support javascript.
loading
Three Novel Spectrin Variants in Jaundiced Neonates.
Christensen, Robert D; Agarwal, Archana M; Yaish, Hassan M; Reading, N Scott; O'Brien, Elizabeth A; Prchal, Josef T.
Afiliação
  • Christensen RD; 1 University of Utah, Salt Lake City, UT, USA.
  • Agarwal AM; 2 Intermountain Healthcare, Salt Lake City, UT, USA.
  • Yaish HM; 1 University of Utah, Salt Lake City, UT, USA.
  • Reading NS; 3 ARUP Laboratories, Salt Lake City, UT, USA.
  • O'Brien EA; 1 University of Utah, Salt Lake City, UT, USA.
  • Prchal JT; 1 University of Utah, Salt Lake City, UT, USA.
Clin Pediatr (Phila) ; 57(1): 19-26, 2018 Jan.
Article em En | MEDLINE | ID: mdl-28090778
Various mutations in the genes encoding alpha spectrin (SPTA1) or beta spectrin (SPTB) are known to cause erythrocyte membrane disorders, sometimes associated with severe neonatal jaundice and anemia. We used a next-generation sequencing panel to evaluate 3 unrelated neonates who had puzzling cases of nonimmune hemolytic jaundice. In each case, we identified novel mutations in either SPTA1 or SPTB. Correlating erythrocyte morphology, clinical course, and computational analysis, we submit that each of the 3 variants is a probable pathogenic cause of the hereditary hemolytic conditions in these patients. We hope other pediatric practitioners caring for neonates with what appears to be idiopathic severe neonatal hyperbilirubinemia will look for spectrin variants as a possible cause, because additional cases with these specific variants along with this clinical phenotype are needed to confirm our postulate that these 3 cases are indeed pathogenic mutations.
Assuntos
Palavras-chave

Texto completo: 1 Coleções: 01-internacional Base de dados: MEDLINE Assunto principal: Esferocitose Hereditária / Espectrina / Eliptocitose Hereditária / Icterícia Neonatal / Mutação Tipo de estudo: Prognostic_studies Limite: Adult / Female / Humans / Male / Newborn Idioma: En Revista: Clin Pediatr (Phila) Ano de publicação: 2018 Tipo de documento: Article País de afiliação: Estados Unidos

Texto completo: 1 Coleções: 01-internacional Base de dados: MEDLINE Assunto principal: Esferocitose Hereditária / Espectrina / Eliptocitose Hereditária / Icterícia Neonatal / Mutação Tipo de estudo: Prognostic_studies Limite: Adult / Female / Humans / Male / Newborn Idioma: En Revista: Clin Pediatr (Phila) Ano de publicação: 2018 Tipo de documento: Article País de afiliação: Estados Unidos