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Ophthalmic Genet ; 33(2): 107-10, 2012 Jun.
Artículo en Inglés | MEDLINE | ID: mdl-22171663

RESUMEN

BACKGROUND: Blepharophimosis, ptosis and epicanthus inversus syndrome (BPES) is a rare autosomal dominant congenital disorder. Mutations in FOXL2, a gene located at 3q23, have been shown to cause the syndrome. We report a girl with BPES with a "de novo" apparently balanced translocation between chromosomes 3 and 15: t(3;15)(q23;q25). MATERIAL AND METHODS: Conventional cytogenetic and CGH array were performed. RESULTS: The karyotype showed an apparently balanced translocation. Molecular studies by array-CGH did not show deletions in the FOXL2 gene; however, a novel 63.2 kb deletion involving a non-protein-coding gene (PISRT1) was found. CONCLUSIONS: The novel deletion found could be involved in FOXL2 regulation and constitutes the smallest deletion described in a female with BPES. In cases of "de novo" apparently balanced translocation, only a 5-6% risk of phenotype alteration is described. Molecular studies can help to discover these alterations and provide insight for genetic counseling.


Asunto(s)
Blefarofimosis/genética , Deleción Cromosómica , Cromosomas Humanos Par 15/genética , Cromosomas Humanos Par 3/genética , Hibridación Genómica Comparativa , Factores de Transcripción Forkhead/genética , ARN no Traducido/genética , Translocación Genética , Blefaroptosis/genética , Preescolar , Análisis Mutacional de ADN , Femenino , Proteína Forkhead Box L2 , Humanos , Cariotipo , ARN Largo no Codificante
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