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Am J Hematol ; 88(11): 948-54, 2013 Nov.
Artículo en Inglés | MEDLINE | ID: mdl-23861223

RESUMEN

SNP array (SNPa) was developed to detect copy number alteration (CNA) and loss of heterozygosity (LOH) without copy number changes, CN-LOH. We aimed to identify novel genomic aberrations using SNPa in 31 WM with paired samples. Methylation status and mutation were analyzed on target genes. A total of 61 genetic aberrations were observed, 58 CNA (33 gains, 25 losses) in 58% of patients and CN-LOH in 6% of patients. The CNA were widely distributed throughout the genome, including 12 recurrent regions and identified new cryptic clonal chromosomal lesions that were mapped. Gene set expression analysis demonstrated a relationship between either deletion 6q or gain of chromosome 4 and alteration of gene expression profiling. We then studied methylation status and sought for mutations in altered regions on target genes. We observed methylation of DLEU7 on chromosome 13 in all patients (n = 12) with WM, and mutations of CD79B/CD79A genes (17q region), a key component of the BCR pathway, in 15% of cases. Most importantly, higher frequency of ≥3 CNA was observed in symptomatic WM. In conclusion, this study expands the view of the genomic complexity of WM, especially in symptomatic WM, including a potentially new mechanism of gene dysfunction, acquired uniparental disomy/CN-LOH. Finally, we have identified new potential target genes in WM, such as DLEU7 and CD79A/B.


Asunto(s)
Aberraciones Cromosómicas , Variaciones en el Número de Copia de ADN , Metilación de ADN , Regulación de la Expresión Génica , Pérdida de Heterocigocidad , Mutación , Macroglobulinemia de Waldenström/genética , Adulto , Anciano , Anciano de 80 o más Años , Antígenos CD79/genética , Antígenos CD79/metabolismo , Deleción Cromosómica , Duplicación Cromosómica , Estudios de Cohortes , Femenino , Francia , Estudio de Asociación del Genoma Completo , Humanos , Masculino , Persona de Mediana Edad , Proteínas de Neoplasias , Proteínas Supresoras de Tumor/genética , Proteínas Supresoras de Tumor/metabolismo , Macroglobulinemia de Waldenström/metabolismo
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