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Turk J Med Sci ; 45(2): 306-12, 2015.
Artículo en Inglés | MEDLINE | ID: mdl-26084119

RESUMEN

BACKGROUND/AIM: Noonan syndrome is an autosomal dominant disorder with an incidence of 1/1000-2500. It results from protein-tyrosine phosphatase, nonreceptor type 11 (PTPN11) mutations in roughly 50% of cases. Mutational screening of PTPN11 has been carried out in different populations. Thus, the aim of this study was to screen, for the first time, PTPN11 mutations in a series of Moroccan Noonan syndrome patients. MATERIALS AND METHODS: We used bidirectional sequencing of exons 3 and 8, considered as PTPN11 mutation hot spots, and then compared the rate of mutational events of these exons between different populations using chi-square and Fisher's exact tests. RESULTS: We detected 3 heterozygous mutations (Asp6lGly, Tyr63Cys, and Asn308Ser) in 4 individuals of 16 sporadic patients (25%). The rate of mutation in our cohort did not differ from that of other populations. However, we found significant differences in the mutation rate of exon 8 between one Japanese cohort and some populations, which requires more investigations to be explained. CONCLUSION: The present study allowed identification of mutations clustered in exons 3 and 8 of the PTPN11 gene in a Moroccan Noonan syndrome cohort and enabled us to give appropriate genetic counseling to the mutation-positive patients.


Asunto(s)
Síndrome de Noonan , Proteína Tirosina Fosfatasa no Receptora Tipo 11/genética , Niño , Preescolar , Femenino , Asesoramiento Genético , Humanos , Masculino , Marruecos , Mutación , Tasa de Mutación , Síndrome de Noonan/diagnóstico , Síndrome de Noonan/genética , Fenotipo
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