Chanarin-Dorfman syndrome: clinical report and novel mutation in ABHD5 gene.
J Postgrad Med
; 60(3): 332-4, 2014.
Article
em En
| MEDLINE
| ID: mdl-25121381
Chanarin-Dorfman syndrome (CDS) is a multisystem, autosomal recessive genetic disorder characterized by congenital non-bullous ichthyosiform erythroderma with accumulation of lipid droplets in granulocytes and basal keratinocytes. An 18-month-old female child presented with typical dermatological features of CDS. She was born as a collodion baby. Liver biopsy showed micronodular cirrhosis along with macrovesicular hepatic steatosis. Sequencing of all exons and exon-intron boundaries of the ABHD5 gene showed that the patient was homozygous for a novel mutation g.24947delG (c.773 + 1delG) in intron 5. This is the first Indian child with mutation proven CDS.
Texto completo:
1
Coleções:
01-internacional
Base de dados:
MEDLINE
Assunto principal:
Eritrodermia Ictiosiforme Congênita
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1-Acilglicerol-3-Fosfato O-Aciltransferase
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Erros Inatos do Metabolismo Lipídico
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Doenças Musculares
Limite:
Female
/
Humans
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Infant
Idioma:
En
Revista:
J Postgrad Med
Ano de publicação:
2014
Tipo de documento:
Article
País de afiliação:
Índia