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Cell Death Dis ; 5: e1250, 2014 May 22.
Artículo en Inglés | MEDLINE | ID: mdl-24853428

RESUMEN

Autism and Alzheimer's disease (AD) are, respectively, neurodevelopmental and degenerative diseases with an increasing epidemiological burden. The AD-associated amyloid-ß precursor protein-α has been shown to be elevated in severe autism, leading to the 'anabolic hypothesis' of its etiology. Here we performed a focused microarray analysis of genes belonging to NOTCH and WNT signaling cascades, as well as genes related to AD and apoptosis pathways in cerebellar samples from autistic individuals, to provide further evidence for pathological relevance of these cascades for autism. By using the limma package from R and false discovery rate, we demonstrated that 31% (116 out of 374) of the genes belonging to these pathways displayed significant changes in expression (corrected P-values <0.05), with mitochondria-related genes being the most downregulated. We also found upregulation of GRIN1, the channel-forming subunit of NMDA glutamate receptors, and MAP3K1, known activator of the JNK and ERK pathways with anti-apoptotic effect. Expression of PSEN2 (presinilin 2) and APBB1 (or F65) were significantly lower when compared with control samples. Based on these results, we propose a model of NMDA glutamate receptor-mediated ERK activation of α-secretase activity and mitochondrial adaptation to apoptosis that may explain the early brain overgrowth and disruption of synaptic plasticity and connectome in autism. Finally, systems pharmacology analyses of the model that integrates all these genes together (NOWADA) highlighted magnesium (Mg(2+)) and rapamycin as most efficient drugs to target this network model in silico. Their potential therapeutic application, in the context of autism, is therefore discussed.


Asunto(s)
Enfermedad de Alzheimer/genética , Trastorno Autístico/genética , Cerebelo/metabolismo , Conectoma , Enfermedad de Alzheimer/tratamiento farmacológico , Enfermedad de Alzheimer/patología , Enfermedad de Alzheimer/fisiopatología , Apoptosis/genética , Trastorno Autístico/tratamiento farmacológico , Trastorno Autístico/patología , Trastorno Autístico/fisiopatología , Cerebelo/efectos de los fármacos , Cerebelo/patología , Cerebelo/fisiopatología , Simulación por Computador , Bases de Datos Genéticas , Diseño de Fármacos , Perfilación de la Expresión Génica/métodos , Regulación de la Expresión Génica , Redes Reguladoras de Genes , Predisposición Genética a la Enfermedad , Humanos , Terapia Molecular Dirigida , Análisis de Secuencia por Matrices de Oligonucleótidos , Fenotipo , Pronóstico , Transducción de Señal/genética , Biología de Sistemas , Transcripción Genética
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