Multiple sulfatase deficiency with early severe retinal degeneration.
J Child Neurol
; 6(3): 229-35, 1991 Jul.
Article
em En
| MEDLINE
| ID: mdl-1875023
We report an unusual case of multiple sulfatase deficiency in which neurodegeneration was accompanied by early, severe visual impairment associated with prominent pigmentary retinopathy, suggesting a diagnosis of neuronal ceroid-lipofuscinosis. The levels of arylsulfatases A, B, and C, heparan N-sulfatase, N-acetylgalactosamine-6-sulfate sulfatase, and iduronate-2-sulfate sulfatase were all markedly decreased in cultured skin fibroblasts. Screening tests for mucopolysacchariduria were consistently negative; however, thin-layer chromatographic analysis of isolated urinary glycosaminoglycans showed increased amounts of heparan sulfate.
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Coleções:
01-internacional
Base de dados:
MEDLINE
Limite:
Child
/
Humans
/
Male
Idioma:
En
Ano de publicação:
1991
Tipo de documento:
Article