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Australas J Dermatol
; 65(3): e45-e49, 2024 May.
Artigo
em Inglês
| MEDLINE
| ID: mdl-38419182
RESUMO
Netherton syndrome (NS) is a rare autosomal recessive genodermatosis. In this article, we present two siblings with NS who harbour a novel variant in the SPINK5 gene and were treated with infliximab infusions. Both patients exhibited the characteristic clinical triad of NS, and their whole exome sequencing analysis revealed a homozygous variant, c.1820+53G>A, in the SPINK5 gene. Notably, this is the first documented instance of homozygosity for this particular variant. Despite the absence of a specific treatment, both patients achieved total clearance of the skin lesions, and a significant decrease in total IgE levels was documented.
Assuntos
Infliximab , Síndrome de Netherton , Inibidor de Serinopeptidase do Tipo Kazal 5 , Feminino , Humanos , Masculino , Fármacos Dermatológicos/uso terapêutico , Homozigoto , Infliximab/uso terapêutico , Síndrome de Netherton/genética , Síndrome de Netherton/tratamento farmacológico , Inibidor de Serinopeptidase do Tipo Kazal 5/genética , Irmãos , Adulto Jovem , Adulto
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